TY - JOUR
T1 - The XIST lncRNA is a sex-specific reservoir of TLR7 ligands in SLE
AU - Crawford, Jonathan D.
AU - Wang, Hong
AU - Trejo-Zambrano, Daniela
AU - Cimbro, Raffaello
AU - Talbot, C. Conover
AU - Thomas, Mekha A.
AU - Curran, Ashley M.
AU - Girgis, Alexander A.
AU - Schroeder, John T.
AU - Fava, Andrea
AU - Goldman, Daniel W.
AU - Petri, Michelle
AU - Rosen, Antony
AU - Antiochos, Brendan
AU - Darrah, Erika
N1 - Publisher Copyright:
Copyright: © 2023, Crawford et al. This is an open access article published under the terms of the Creative Commons Attribution 4.0 International License.
PY - 2023/10
Y1 - 2023/10
N2 - Systemic lupus erythematosus (SLE) is a systemic autoimmune disease with a dramatic sex bias, affecting 9 times more women than men. Activation of Toll-like receptor 7 (TLR7) by self-RNA is a central pathogenic process leading to aberrant production of type I interferon (IFN) in SLE, but the specific RNA molecules that serve as TLR7 ligands have not been defined. By leveraging gene expression data and the known sequence specificity of TLR7, we identified the female-specific X-inactive specific transcript (XIST) long noncoding RNA as a uniquely rich source of TLR7 ligands in SLE. XIST RNA stimulated IFN-α production by plasmacytoid DCs in a TLR7-dependent manner, and deletion of XIST diminished the ability of whole cellular RNA to activate TLR7. XIST levels were elevated in blood leukocytes from women with SLE compared with controls, correlated positively with disease activity and the IFN signature, and were enriched in extracellular vesicles released from dying cells in vitro. Importantly, XIST was not IFN inducible, suggesting that XIST is a driver, rather than a consequence, of IFN in SLE. Overall, our work elucidated a role for XIST RNA as a female sex-specific danger signal underlying the sex bias in SLE.
AB - Systemic lupus erythematosus (SLE) is a systemic autoimmune disease with a dramatic sex bias, affecting 9 times more women than men. Activation of Toll-like receptor 7 (TLR7) by self-RNA is a central pathogenic process leading to aberrant production of type I interferon (IFN) in SLE, but the specific RNA molecules that serve as TLR7 ligands have not been defined. By leveraging gene expression data and the known sequence specificity of TLR7, we identified the female-specific X-inactive specific transcript (XIST) long noncoding RNA as a uniquely rich source of TLR7 ligands in SLE. XIST RNA stimulated IFN-α production by plasmacytoid DCs in a TLR7-dependent manner, and deletion of XIST diminished the ability of whole cellular RNA to activate TLR7. XIST levels were elevated in blood leukocytes from women with SLE compared with controls, correlated positively with disease activity and the IFN signature, and were enriched in extracellular vesicles released from dying cells in vitro. Importantly, XIST was not IFN inducible, suggesting that XIST is a driver, rather than a consequence, of IFN in SLE. Overall, our work elucidated a role for XIST RNA as a female sex-specific danger signal underlying the sex bias in SLE.
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U2 - 10.1172/jci.insight.169344
DO - 10.1172/jci.insight.169344
M3 - Article
C2 - 37733447
AN - SCOPUS:85176508257
SN - 2379-3708
VL - 8
JO - JCI Insight
JF - JCI Insight
IS - 20
M1 - e169344
ER -